J Arthropod-Borne Dis, December 2019, 13(4): 416–419 MH Aelami et al.: Urinary Canthariasis … 416 http://jad.tums.ac.ir Published Online: December 31, 2019 Case Report Urinary Canthariasis Due to Tenebrio molitor Larva in a Ten-Year-Old Boy Mohammad Hassan Aelami1; Alireza Khoei2; Hamidreza Ghorbani3; Farrokh Seilanian- Toosi4; Elham Poustchi5; Bibi Razieh Hosseini-Farash5,6; *Elham Moghaddas5 1Department of Pediatrics and Hand Hygiene and Infection Control Research Center, Imam Reza Hospital, Mashhad University of medical Sciences, Mashhad, Iran 2Department of Pathology, Faculty of Medicine, Mashhad University of Medical Sciences, Mashhad, Iran 3Kidney Transplantation Complications Research Center, Mashhad University of Medical Sciences, Mashhad, Iran 4Department of Radiology, Faculty of Medicine, Mashhad University of Medical Sciences, Mashhad, Iran 5Department of Parasitology and Mycology, Faculty of Medicine, Mashhad University of Medical Sciences, Mashhad, Iran 6Cutaneous Leishmaniasis Research Center, Mashhad University of Medical Sciences, Mashhad, Iran (Received 10 Aug 2018; accepted 26 Oct 2019) Abstract Canthariasis is a human disease caused by infestation of beetle larvae. We report here an unusual cause of urogenital in- fection due to Tenebrio molitor in a 10-year-old boy suffering from severe and intermittent suprapubic pain from Nehban- dan City, Northeastern Iran in 2018. After 9 months, three larvae were excreted. Keratinization of bladder wall was ob- served in histopathology. All laboratory evaluations were normal except for presence of microscopic hematuria. This re - port implicated that T. molitor could infest bladder accidentally and cause canthariasis and clinical symptoms that may lead to severe pain and bladder inflammation and hyperemia. Keywords: Canthariasis; Bladder; Human; Child Introduction Canthariasis is a parasitic disease caused by beetle larvae, either humans or animals (1). Can- thariasis in humans and animals due to Teneb- rio molitor is an uncommon phenomenon. The reports are very rare and pathological effects are poorly known (2). The first and only report on canthariasis due to T. molitor in bladder was reported about 375 years ago in a book entitled “Observations Medi- cae” (3). Moreover, T. molitor has invaded um- bilicus and tonsils (4). However, the majority of reported cases of T. molitor larva in hu- mans have been related to gastrointestinal tract (2, 5). Recently accidental ulcer infestation due T. molitor has been reported in a case with HIV/AIDS and skin ulcers (6). Tenebrio molitor is a yellow mealworm commonly found as a stored-product pest. The life cycle of this organism comprises four stages including egg, larva, pupa and adult forms. The entire life cycle lasts approximately one year. Adult and the larvae feed on grains (hence the name mealworm), meat or decomposing ani- mals including birds, spiders, rodents, lizards and some other beetles. Human is infected by the ingestion of eggs or larvae of T. molitor (7). Tenebrio molitor can also promote allergic re- actions in exposed individuals (8). Epidermolysis bullosa (EB) is the name for a group of rare genetic skin disorders that cause fragility in skin. Any trauma or friction to the skin can cause painful blisters (9). In this case report, we describe an unusu- al case of canthariasis due to T. molitor in a 10-year-old boy with EB. *Corresponding author: Dr Elham Moghaddas, E-mail: moghaddase@mums.ac.ir http://jad.tums.ac.ir/ J Arthropod-Borne Dis, December 2019, 13(4): 416–419 MH Aelami et al.: Urinary Canthariasis … 417 http://jad.tums.ac.ir Published Online: December 31, 2019 Case presentation The patient was a 10-year-old boy (23kg) who had epidermolysis bullosa (EB) disorder referred from a local clinic from Nehbandan City in 2018, Northeastern of Iran. He suffered from periodic painful episodes in urinary sys- tem for the past 9 months. Symptoms were in- termittent, and urine contained brown sediments similar to bladder stones (Fig. 1). There were no signs of gross hematuria and fever during the mentioned time. Complete medical exami- nations including urine analysis, urine culture, urine and blood biochemistry, hematology, Im- munoassays for autoimmune diseases, thyroid function tests and renal ultrasound were per- formed. Ultrasound was performed after observa- tion of the excreted brown sediment from ure- thra for finding kidney stones. Kidney and blad- der appeared normal in ultrasound. Urinalysis revealed no abnormality except for occult blood. Urinary culture was negative. Blood cell count and creatinine levels showed the normal rang- es. Moreover, urine biochemistry was normal. Erythrocyte sedimentation rate (ESR) was 21 mm/1h. The boy’s mother found three larvae in his urine more than two weeks after symptoms start. Morphologically, the larvae had six short legs close together near the head. The head has a pair of short hooks and was creamy white in color. The larvae had 26mm length and 0.5 mm width. They had three pairs of feet on the belly near the head and with each foot had 4 sections and nodes hocks curved claws (Fig. 2). Based on the characteristics, the larva was diagnosed as T. molitor. Debris, hyperemia and inflammation were identified in bladder and in the urethra cystos- copy (Fig. 3). However, no larva was seen in bladder and urethra. A single dose of 3mg of ivermectin was orally administrated. The pa- tient recovered after oral Ivermectin therapy. Following treatment, high volume of insect shells was repulsed (Fig. 4). In addition, the abdominal pain completely resolved within a few months following treatment. Histopathol- ogy of excreted particles from urethral duct showed keratinizing squamous metaplasia af- ter treatment. Informed consent was taken from the pa- tient’s parents. This study was reviewed and approved by the Ethics Committees of Mash- had University of Medical Sciences, Iran. Fig. 1. Brown sedimentations excreted via urethra Fig. 2. Macroscopic examination of the larva http://jad.tums.ac.ir/ J Arthropod-Borne Dis, December 2019, 13(4): 416–419 MH Aelami et al.: Urinary Canthariasis … 418 http://jad.tums.ac.ir Published Online: December 31, 2019 Fig. 3. Cystoscopy finding including debris, hypere- mia and inflammation Fig. 4. Disposal shell of insect after treatment by ivermectine Discussion This case was initially misdiagnosed as kid- ney stones because the shedding of stone like substance without excretion of any larva from the urethra. Ultrasonography failed to detect the larva probably because the initial request was ordered for checking of kidney or urinary tract stones. Unlike most stones that are hard, the ob- served particles from this patient had soft struc- ture. This beetle has 9–20 instars, the brown sed- imentations were probably larvae shells during molting (https://en.wikipedia.org/wiki/Mealworm). On the other hand, we could speculate that the class of the scanner for determination of lar- vae was inadequate. Beetle larvae have been recovered from hu- man organs including tonsils (4), nose and blad- der (10), umbilical cord (11), the gastrointesti- nal tract (4, 5), as well as from subcutaneous tissue in wild bird (1). Canthariasis is a rare ectoparasitic condition. Among the reported cases, most of them were gastrointestinal. No previous cases in HIV/AIDS patients have been reported, neither associated with skin ulcers. Beetles could be found in hous- es where dried grains are stored, particularly this is case for T. molitor. Adult Tenebrio laid eggs on the skin of our patient. Females lay eggs and larvae develop within few weeks at necrotic tissue. In fact, scars attract the beetle and its lar- vae are fed on a variety of dried plant or ani- mal matter and are known to scavenge on car- casses of dead animals. Moreover, canthariasis has been reported in a case with HIV/AIDS patients associated with skin ulcer (6). Ulcers in HIV patients and other diseases related to skin damages could increase susceptibility to a wide range of infections such as canthariasis. The present case had EB is a genetic dis- order that result in easy blistering of the skin and mucous membranes. The patients with EB are susceptible to infection due to damage in skin physical barrier (9). Beetles are a common household pest found in stored grain and stored food products. Adult of T. molitor laid eggs on the in or around the urogenital opening of our patient when he was resting. Then, the eggs hatch and larvae mi- grate along the urethra with consequent cantha- riasis. Some previous studies suggested this route of transmission for urinary myiasis (12,13) This larva is unable to dwell in subsequently of the bladder wall. Because of this, our patient showed no macroscopic hematuria, and the blad- der wall thickness was also normal (3mm). How- ever, because of long stimulation time, wall bladder showed pathological changes. There were no lesion(s) in radiographic investigation. Tenebrio molitor can be the intermediate hosts of the rat tapeworm, Hymenolepis diminu- http://jad.tums.ac.ir/ https://en.wikipedia.org/wiki/Mealworm J Arthropod-Borne Dis, December 2019, 13(4): 416–419 MH Aelami et al.: Urinary Canthariasis … 419 http://jad.tums.ac.ir Published Online: December 31, 2019 ta (4). On the other hand, human is the acci- dental host of H. diminuta by ingestion of bee- tles or meal worms containing metacestode. Up to now, seven human patients have been re- ported from Iran to be infected with H. diminuta (14). Therefore, unintentional swallowing of T. molitor may be a possible route of transmission. Conclusion Infection with T. molitor can present as an emergency condition with acute pain episodes in urinary system. Understanding of this infec- tion should be considered when there are no ev- ident signs for stones in urinary system in routine management. Acknowledgements We appreciate the patient's parents and their child for their support at all stages of the diagnosis of disease. The authors declare that there is no con- flict of interests. References 1. Park BK, Park SJ, Ryu SY, Chae JS, Park J, Choi KS (2016) Subcutaneous cantha- riasis due to Tenebrio molitor larva (Col- eoptera: Tenebrionidae) in Egretta inter- media. J Dair Vet Anim Res. 3: 00086. 2. Palmer ED (1946) Intestinal canthariasis due to Tenebrio molitor. J Parasitol. 32: 32–54. 3. Finke MD (2002) Complete nutrient compo- sition of commercially raised invertebrates used as food for insectivores. Zoo Biol. 21: 269–285. 4. Hinman EH, Faust EC (1932) The inges- tion of the larvae of Tenebrio molitor, L. (Meal Worm) by man. J Parasitol. 19: 119–120. 5. Senior-White RA (1920) On the occurrence of Coleóptera in the human intestine. In dian J Med Res. 7: 568–569. 6. Mullen GR, Durden LA (2009) Medical and Veterinary Entomology. Academic Press, New York. 7. Freye HB, Esch RE, Litwin CM, Sorkin L (1996) Anaphylaxis to the ingestion and inhalation of Tenebrio molitor (mealworm) and Zophobas morio (superworm). Al- lergy Asthma Pro. 17: 215–219. 8. Tulp N (1739) Observationes Medicae. Wishoff G, Leiden. 9. Bateman T (1811) An account of the larvae of two species of insects discharged from the human body. Edinburgh Med Surg J. 7: 41–48. 10. Mowlavi G, Mobedi I, Mamishi S, Re- zaeian M, Ashtiani MH, Kashi M (2008) Hymenolepis diminuta (Rodolphi, 1819) infection in a child from Iran. Iran J Publ Health. 37: 120–122. 11. 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